Tooth transplantation in cherubism and incontinentia pigmenti: report of two unusual cases

摘要

In children, autotransplantation has been an accepted treatment alternative in the Scandinavian countries for decades in cases of agenesis or trauma. When working with children with rare syndromes, lack of teeth is often so pronounced that there are no teeth available lor transplantation, tven so, sometimes there are retained teeth that can be transplanted! Here we present two patients with rare syndromes in which a retained tooth was transplanted. In both cases, neither the donor tooth nor the recipient site was ideal for transplantation. The first case is a girl with incontinentia pigmenti, 15 years old at the time of transplantation, and the second case is a boy with severe cherubism, aged 9.5 years at the lime of transplantation. In the first case, a second molar with multiple roots retained at a mesial angle to the first molar in the upper jaw was transplanted to an infected site. In the second case, a retained first premolar in the upper jaw was transplanted to a cystic lesion. In both patients, the profit in the event of a successful transplantation was so great, that an attempt was made in spite of the negative circumstances. Both teeth were successfully transplanted and have been followed for more than 2 years with no anky-losis or pulp necrosis developing. We conclude that in a child with multiple missing teeth, the conventional rules of transplantation may be stretched.